Frosted Branch Angiitis as Ocular Manifestation of Behçet’s Disease: Unusual Case Report and Literature Review
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We report an unusual case of unilateral frosted branch angiitis associated with Behçet’s disease, includinga review of previously reported cases. A 39-year-old male with history of recurrent oral and genitalulcers presented with visual loss in his left eye. Fundus findings demonstrated occlusive retinal vasculitisresembling acute frosted branch angiitis. Laboratory examinations including viral markers revealed noabnormal findings except positive HLA-B51. The patient was treated with systemic steroid and cyclosporine. Six months after presentation, new oral ulcers and pseudofolliculitis appeared, and he was diagnosedwith Behçet’s disease following rheumatology consultation. During follow-up, there was no change invisual acuity of hand movement, and disc neovascularization developed even after complete panretinalphotocoagulation. Ocular manifestations of Behçet’s disease can present as unilateral frosted branchangiitis, and may consecutively involve in both eyes. Early immunosuppressive treatment is recommended
Abstract
We report an unusual case of unilateral frosted branch angiitis associated with Behçet’s disease, includinga review of previously reported cases. A 39-year-old male with history of recurrent oral and genitalulcers presented with visual loss in his left eye. Fundus findings demonstrated occlusive retinal vasculitisresembling acute frosted branch angiitis. Laboratory examinations including viral markers revealed noabnormal findings except positive HLA-B51. The patient was treated with systemic steroid and cyclosporine. Six months after presentation, new oral ulcers and pseudofolliculitis appeared, and he was diagnosedwith Behçet’s disease following rheumatology consultation. During follow-up, there was no change invisual acuity of hand movement, and disc neovascularization developed even after complete panretinalphotocoagulation. Ocular manifestations of Behçet’s disease can present as unilateral frosted branchangiitis, and may consecutively involve in both eyes. Early immunosuppressive treatment is recommended
참고문헌 (11)
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