성문하 병변으로 확인된 화골성 기관증 환자 1예
A Case of Tracheobronchopathia Osteochondroplastica Confirmed With a Subglottic Lesion
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초록
Tracheobronchopathia osteochondroplastica (TO) is rare idiopathic abnormality with incidence of 0.2%–0.7% from bronchoscopy. TO is characterized by focal or diffuse development of osseous and/or cartilaginous nodule in the submucosa of the trachea and bronchial walls. Most of the cases are asymptomatic, and if present, they can be nonspecific and diverse, such coughing and wheezing. Bronchoscopy and radiographic studies are useful diagnostic tool and conservative therapy is needed for each symptoms. Author reports a case of 49-year-old male who presented with throat discomfort without any significant past medical history. A subglottic nodular lesion with ulceration was identified, and laryngeal microsurgery for biopsy was done to rule out Tb or subglottic malignancy. However, the histopathological findings were indicative of TO, then we consult for bronchoscopy to confirm the diagnosis. Bronchoscopy also revealed consistent findings with TO. The patient is currently under conservative management and observation, without the need for further surgical intervention.
Abstract
Tracheobronchopathia osteochondroplastica (TO) is rare idiopathic abnormality with incidence of 0.2%–0.7% from bronchoscopy. TO is characterized by focal or diffuse development of osseous and/or cartilaginous nodule in the submucosa of the trachea and bronchial walls. Most of the cases are asymptomatic, and if present, they can be nonspecific and diverse, such coughing and wheezing. Bronchoscopy and radiographic studies are useful diagnostic tool and conservative therapy is needed for each symptoms. Author reports a case of 49-year-old male who presented with throat discomfort without any significant past medical history. A subglottic nodular lesion with ulceration was identified, and laryngeal microsurgery for biopsy was done to rule out Tb or subglottic malignancy. However, the histopathological findings were indicative of TO, then we consult for bronchoscopy to confirm the diagnosis. Bronchoscopy also revealed consistent findings with TO. The patient is currently under conservative management and observation, without the need for further surgical intervention.
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